Similar clinical and neuroimaging features in monozygotic twin pair with mutation in progranulin

Neurology. 2012 Apr 17;78(16):1245-9. doi: 10.1212/WNL.0b013e318251594c. Epub 2012 Apr 4.

Abstract

Objective: To report the phenotypic characterization of monozygotic twins with mutations encoding progranulin (PGRN).

Methods: We studied a twin pair with an exon 4 gene deletion in the PGRN gene. Both twins had clinical and neuropsychological examinations as well as structural MRI and fluorodeoxyglucose PET (FDG-PET) scans. PGRN gene sequencing was performed followed by progranulin ELISA in plasma.

Results: Both twins manifested symptoms within 3 years of each other, with early behavioral, language, dysexecutive, and memory problems. MRI and FDG-PET imaging demonstrated a strikingly similar topography of findings with clear left hemisphere predominance. Serum progranulin levels in both were well below those from a normal population sample.

Conclusions: Compared with the heterogeneity seen in many families with PGRN mutations, these monozygotic twins demonstrated strong clinical, neuroimaging, and serum progranulin level similarities, demonstrating the importance of shared genetic profiles beyond environmental influences in the symptomatic expression of the disease.

Publication types

  • Case Reports
  • Research Support, N.I.H., Extramural
  • Research Support, Non-U.S. Gov't
  • Twin Study

MeSH terms

  • Brain / metabolism
  • Dominance, Cerebral / genetics
  • Exons / genetics
  • Fluorodeoxyglucose F18*
  • Frontotemporal Dementia / genetics*
  • Frontotemporal Dementia / psychology*
  • Gene Deletion
  • Genetic Predisposition to Disease / genetics
  • Humans
  • Intercellular Signaling Peptides and Proteins / blood
  • Intercellular Signaling Peptides and Proteins / genetics*
  • Magnetic Resonance Imaging / methods
  • Magnetic Resonance Imaging / psychology
  • Male
  • Middle Aged
  • Neuroimaging / methods
  • Neuroimaging / psychology*
  • Neuropsychological Tests / statistics & numerical data
  • Phenotype
  • Positron-Emission Tomography / methods
  • Positron-Emission Tomography / psychology
  • Progranulins
  • Radiopharmaceuticals
  • Twins, Monozygotic / genetics*
  • Twins, Monozygotic / psychology*

Substances

  • GRN protein, human
  • Intercellular Signaling Peptides and Proteins
  • Progranulins
  • Radiopharmaceuticals
  • Fluorodeoxyglucose F18