Natural history of gastro-entero-pancreatic and thoracic neuroendocrine tumors. Data from a large prospective and retrospective Italian epidemiological study: the NET management study

J Endocrinol Invest. 2012 Oct;35(9):817-23. doi: 10.3275/8102. Epub 2011 Nov 9.

Abstract

Background: The few epidemiological data available in literature on neuroendocrine tumors (NET) are mainly based on Registry databases, missing therefore details on their clinical and natural history.

Aim: To investigate epidemiology, clinical presentation, and natural history of NET.

Design and setting: A large national retrospective survey was conducted in 13 Italian referral centers. Among 1203 NET, 820 originating in the thorax (T-NET), in the gastro-enteropancreatic tract (GEP-NET) or metastatic NET of unknown primary origin (U-NET) were enrolled in the study.

Results: 93% had a sporadic and 7% a multiple endocrine neoplasia type 1 (MEN1)-associated tumor; 63% were GEP-NET, 33% T-NET, 4% U-NET. Pancreas and lung were the commonest primary sites. Poorly differentiated carcinomas were <10%, all sporadic. The incidence of NET had a linear increase from 1990 to 2007 in all the centers. The mean age at diagnosis was 60.0 ± 16.4 yr, significantly anticipated in MEN1 patients (47.7 ± 16.5 yr). Association with cigarette smoking and other non-NET cancer were more prevalent than in the general Italian population. The first symptoms of the disease were related to tumor burden in 46%, endocrine syndrome in 23%, while the diagnosis was fortuity in 29%. Insulin (37%) and serotonin (35%) were the most common hormonal hypersecretions. An advanced tumor stage was found in 42%, more frequently in the gut and thymus. No differences in the overall survival was observed between T-NET and GEP-NET and between sporadic and MEN1-associated tumors at 10 yr from diagnosis, while survival probability was dramatically reduced in U-NET.

Conclusions: The data obtained from this study furnish relevant information on epidemiology, natural history, and clinico-pathological features of NET, not available from the few published Register studies.

Publication types

  • Multicenter Study
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adolescent
  • Adult
  • Aged
  • Aged, 80 and over
  • Child
  • Child, Preschool
  • Disease Management
  • Female
  • Humans
  • Infant
  • Intestinal Neoplasms / epidemiology*
  • Intestinal Neoplasms / mortality
  • Intestinal Neoplasms / therapy
  • Italy / epidemiology
  • Male
  • Middle Aged
  • Multiple Endocrine Neoplasia Type 1 / epidemiology*
  • Multiple Endocrine Neoplasia Type 1 / mortality
  • Multiple Endocrine Neoplasia Type 1 / therapy
  • Neuroendocrine Tumors / epidemiology*
  • Neuroendocrine Tumors / mortality
  • Neuroendocrine Tumors / therapy
  • Pancreatic Neoplasms / epidemiology*
  • Pancreatic Neoplasms / mortality
  • Pancreatic Neoplasms / therapy
  • Prevalence
  • Prognosis
  • Prospective Studies
  • Retrospective Studies
  • Stomach Neoplasms / epidemiology*
  • Stomach Neoplasms / mortality
  • Stomach Neoplasms / therapy
  • Survival Rate
  • Thoracic Neoplasms / epidemiology*
  • Thoracic Neoplasms / mortality
  • Thoracic Neoplasms / therapy
  • Young Adult

Supplementary concepts

  • Gastro-enteropancreatic neuroendocrine tumor